Custom drug targets rare genetic brain disease in First-Ever human test

NCT ID NCT06706388

First seen Jun 24, 2026 · Last updated Jun 27, 2026 · Updated 1 time

Summary

This study tests a custom-made drug called an antisense oligonucleotide (ASO) designed for one person with dentatorubral-pallidoluysian atrophy (DRPLA), a rare genetic disorder that affects movement and brain function. The drug aims to reduce the harmful effects of the mutated ATN1 gene. The single participant will be monitored for changes in ataxia (loss of muscle control), seizures, and quality of life over two years.

What this could mean

Our plain-language read of the trial. This is informational only — not medical advice or a prediction.

Active substance
personalized antisense oligonucleotide (nL-ATN1-002)
What this could lead to
If it works, this could point toward a treatment for DRPLA, a rare and severe genetic brain disorder.
What could go wrong
This is an early-stage, single-participant study, so results may not apply to others. The drug is experimental and risks are unknown.

This is an AI summary of the original study and may miss details. Read our disclaimer.

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Conditions

The condition(s) this trial relates to.

As listed by the trial registrant

The condition terms exactly as the trial's registrant entered them.

Contacts and locations

Locations

  • Columbia University

    New York, New York, 10027, United States

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Other studies related to the condition(s) this trial covers.